Artículo

Hereditary Amyloidosis: Insights Into a Fibrinogen A Variant Protein

Cattaneo, Elizabeth Renee Icon; Gisonno, Romina Antonela Icon; Abba, Martín Carlos Icon; Santana, Marianela Icon; Rosu, Silvana Antonia Icon; Nucifora, Elsa Mercedes ; Aguirre, Maria Adela ; Giordani, María C. ; Tricerri, Maria Alejandra Icon; Ramella, Nahuel Icon

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Fecha

07/2024

Editorial

Wiley-liss, div John Wiley & Sons Inc.

Revista

Proteins: Structure, Function And Genetics

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Nombre del evento

Fecha del evento

Institución organizadora

ISSN

0887-3585

eISSN

ISBN

Idioma

Inglés

Tipo del evento

Resumen

Amyloidosis are a group of diseases in which soluble proteins aggregate and deposit in fibrillar conformation extracellularly intissues. The effectiveness of therapeutic strategies depends on the specific protein involved, being crucial to accurately determineits nature. Moreover, following the diagnosis, the search for the mutation within relatives allows the clinical advice. Here wereport the precise diagnosis and explored the possible reasons of the structural pathogenicity for a renal amyloidosis related toa fibrinogen Aα-chain variant. Whole-exome sequencing and GATK calling pipeline were leveraged to characterize the proteinvariant present in a patient with kidney failure. Bioinformatics strategies were applied to suggest potential explanations of thevariants aggregation. Our pipeline allowed the identification of a single-point variant of fibrinogen Aα-chain, which opened thepossibility of curative transplantation. In silico structural analysis suggested that the pathogenicity of the variant may be attrib-uted to a heightened susceptibility to yield a peptide prone to deposit as an oligomer with a β-sheet structure. Exploiting the com-prehensive coverage of whole-genome sequencing, we managed to fill a vacant stage in the diagnosis of hereditary amyloidosisand to stimulate the advancement in biomedicine.

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