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dc.contributor.author
Ghani, Mahdi  
dc.contributor.author
Lang, Anthony E.  
dc.contributor.author
Zinman, Lorne  
dc.contributor.author
Nacmias, Benedetta  
dc.contributor.author
Sorbi, Sandro  
dc.contributor.author
Bessi, Valentina  
dc.contributor.author
Tedde, Andrea  
dc.contributor.author
Tartaglia, Maria Carmela  
dc.contributor.author
Surace, Ezequiel Ignacio  
dc.contributor.author
Sato, Christine  
dc.contributor.author
Moreno, Danielle  
dc.contributor.author
Xi, Zhengrui  
dc.contributor.author
Hung, Rachel  
dc.contributor.author
Nalls, Mike A.  
dc.contributor.author
Singleton, Andrew  
dc.contributor.author
George Hyslop, Peter St.  
dc.contributor.author
Savchenko, Ekaterina  
dc.date.available
2019-10-07T18:27:49Z  
dc.date.issued
2015-01  
dc.identifier.citation
Ghani, Mahdi; Lang, Anthony E.; Zinman, Lorne; Nacmias, Benedetta; Sorbi, Sandro; et al.; Mutation analysis of patients with neurodegenerative disorders using NeuroX array; Elsevier Science Inc; Neurobiology of Aging; 36; 1; 1-2015; 545.e9-545.e14  
dc.identifier.issn
0197-4580  
dc.identifier.uri
http://hdl.handle.net/11336/85292  
dc.description.abstract
Genetic analyses of patients with neurodegenerative disorders have identified multiple genes that need to be investigated for the presence of damaging variants. However, mutation analysis by Sanger sequencing is costly and time consuming. We tested the utility of a recently designed semi-custom genome-wide array (NeuroX; Illumina, Inc) tailored to study neurodegenerative diseases (e.g., mutation screening). We investigated 192 patients with 4 different neurodegenerative disorders for the presence of rare damaging variations in 77 genes implicated in these diseases. Several causative mutations were identified and confirmed by Sanger sequencing, including PSEN1 p.M233T responsible for Alzheimer's disease in a large Italian family, as well as SOD1 p.A4V and p.I113T in patients with amyotrophic lateral sclerosis. In total, we identified 78 potentially damaging rare variants (frequency <1%), including ABCA7 p.L400V in a family with Alzheimer's disease and LRRK2 p.R1514Q in 6 of 98 patients with Parkinson's disease (6.1%). In conclusion, NeuroX appears to be helpful for rapid and accurate mutation screening, although further development may be still required to improve some current caveats.  
dc.format
application/pdf  
dc.language.iso
eng  
dc.publisher
Elsevier Science Inc  
dc.rights
info:eu-repo/semantics/openAccess  
dc.rights.uri
https://creativecommons.org/licenses/by-nc-nd/2.5/ar/  
dc.subject
MUTATION  
dc.subject
NEURODEGENERATIVE DISORDER  
dc.subject
NEUROX  
dc.subject.classification
Genética Humana  
dc.subject.classification
Medicina Básica  
dc.subject.classification
CIENCIAS MÉDICAS Y DE LA SALUD  
dc.title
Mutation analysis of patients with neurodegenerative disorders using NeuroX array  
dc.type
info:eu-repo/semantics/article  
dc.type
info:ar-repo/semantics/artículo  
dc.type
info:eu-repo/semantics/publishedVersion  
dc.date.updated
2019-10-07T17:57:13Z  
dc.journal.volume
36  
dc.journal.number
1  
dc.journal.pagination
545.e9-545.e14  
dc.journal.pais
Países Bajos  
dc.journal.ciudad
Amsterdam  
dc.description.fil
Fil: Ghani, Mahdi. University of Toronto; Canadá  
dc.description.fil
Fil: Lang, Anthony E.. University of Toronto; Canadá. Toronto Western Hospital; Canadá  
dc.description.fil
Fil: Zinman, Lorne. University of Toronto; Canadá. Sunnybrook Health Sciences Centre; Canadá  
dc.description.fil
Fil: Nacmias, Benedetta. Università degli Studi di Firenze; Italia  
dc.description.fil
Fil: Sorbi, Sandro. Università degli Studi di Firenze; Italia  
dc.description.fil
Fil: Bessi, Valentina. Università degli Studi di Firenze; Italia  
dc.description.fil
Fil: Tedde, Andrea. Università degli Studi di Firenze; Italia  
dc.description.fil
Fil: Tartaglia, Maria Carmela. University of Toronto; Canadá  
dc.description.fil
Fil: Surace, Ezequiel Ignacio. Consejo Nacional de Investigaciones Científicas y Técnicas; Argentina. Fundación para la Lucha Contra las Enfermedades Neurológicas de la Infancia. Instituto de Investigaciones Neurológicas "Raúl Carrea"; Argentina  
dc.description.fil
Fil: Sato, Christine. University of Toronto; Canadá  
dc.description.fil
Fil: Moreno, Danielle. University of Toronto; Canadá  
dc.description.fil
Fil: Xi, Zhengrui. University of Toronto; Canadá  
dc.description.fil
Fil: Hung, Rachel. University of Toronto; Canadá  
dc.description.fil
Fil: Nalls, Mike A.. National Institute on Aging; Estados Unidos  
dc.description.fil
Fil: Singleton, Andrew. National Institute on Aging; Estados Unidos  
dc.description.fil
Fil: George Hyslop, Peter St.. University of Toronto; Canadá. University of Cambridge; Reino Unido  
dc.description.fil
Fil: Savchenko, Ekaterina. University of Toronto; Canadá  
dc.journal.title
Neurobiology of Aging  
dc.relation.alternativeid
info:eu-repo/semantics/altIdentifier/doi/http://dx.doi.org/10.1016/j.neurobiolaging.2014.07.038  
dc.relation.alternativeid
info:eu-repo/semantics/altIdentifier/url/https://www.sciencedirect.com/science/article/pii/S0197458014005077  
dc.relation.alternativeid
info:eu-repo/semantics/altIdentifier/url/https://www.ncbi.nlm.nih.gov/pmc/articles/PMC4268030/