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dc.contributor.author
Ghani, Mahdi
dc.contributor.author
Lang, Anthony E.
dc.contributor.author
Zinman, Lorne
dc.contributor.author
Nacmias, Benedetta
dc.contributor.author
Sorbi, Sandro
dc.contributor.author
Bessi, Valentina
dc.contributor.author
Tedde, Andrea
dc.contributor.author
Tartaglia, Maria Carmela
dc.contributor.author
Surace, Ezequiel Ignacio

dc.contributor.author
Sato, Christine
dc.contributor.author
Moreno, Danielle
dc.contributor.author
Xi, Zhengrui
dc.contributor.author
Hung, Rachel
dc.contributor.author
Nalls, Mike A.
dc.contributor.author
Singleton, Andrew
dc.contributor.author
George Hyslop, Peter St.
dc.contributor.author
Savchenko, Ekaterina

dc.date.available
2019-10-07T18:27:49Z
dc.date.issued
2015-01
dc.identifier.citation
Ghani, Mahdi; Lang, Anthony E.; Zinman, Lorne; Nacmias, Benedetta; Sorbi, Sandro; et al.; Mutation analysis of patients with neurodegenerative disorders using NeuroX array; Elsevier Science Inc; Neurobiology of Aging; 36; 1; 1-2015; 545.e9-545.e14
dc.identifier.issn
0197-4580
dc.identifier.uri
http://hdl.handle.net/11336/85292
dc.description.abstract
Genetic analyses of patients with neurodegenerative disorders have identified multiple genes that need to be investigated for the presence of damaging variants. However, mutation analysis by Sanger sequencing is costly and time consuming. We tested the utility of a recently designed semi-custom genome-wide array (NeuroX; Illumina, Inc) tailored to study neurodegenerative diseases (e.g., mutation screening). We investigated 192 patients with 4 different neurodegenerative disorders for the presence of rare damaging variations in 77 genes implicated in these diseases. Several causative mutations were identified and confirmed by Sanger sequencing, including PSEN1 p.M233T responsible for Alzheimer's disease in a large Italian family, as well as SOD1 p.A4V and p.I113T in patients with amyotrophic lateral sclerosis. In total, we identified 78 potentially damaging rare variants (frequency <1%), including ABCA7 p.L400V in a family with Alzheimer's disease and LRRK2 p.R1514Q in 6 of 98 patients with Parkinson's disease (6.1%). In conclusion, NeuroX appears to be helpful for rapid and accurate mutation screening, although further development may be still required to improve some current caveats.
dc.format
application/pdf
dc.language.iso
eng
dc.publisher
Elsevier Science Inc

dc.rights
info:eu-repo/semantics/openAccess
dc.rights.uri
https://creativecommons.org/licenses/by-nc-nd/2.5/ar/
dc.subject
MUTATION
dc.subject
NEURODEGENERATIVE DISORDER
dc.subject
NEUROX
dc.subject.classification
Genética Humana

dc.subject.classification
Medicina Básica

dc.subject.classification
CIENCIAS MÉDICAS Y DE LA SALUD

dc.title
Mutation analysis of patients with neurodegenerative disorders using NeuroX array
dc.type
info:eu-repo/semantics/article
dc.type
info:ar-repo/semantics/artículo
dc.type
info:eu-repo/semantics/publishedVersion
dc.date.updated
2019-10-07T17:57:13Z
dc.journal.volume
36
dc.journal.number
1
dc.journal.pagination
545.e9-545.e14
dc.journal.pais
Países Bajos

dc.journal.ciudad
Amsterdam
dc.description.fil
Fil: Ghani, Mahdi. University of Toronto; Canadá
dc.description.fil
Fil: Lang, Anthony E.. University of Toronto; Canadá. Toronto Western Hospital; Canadá
dc.description.fil
Fil: Zinman, Lorne. University of Toronto; Canadá. Sunnybrook Health Sciences Centre; Canadá
dc.description.fil
Fil: Nacmias, Benedetta. Università degli Studi di Firenze; Italia
dc.description.fil
Fil: Sorbi, Sandro. Università degli Studi di Firenze; Italia
dc.description.fil
Fil: Bessi, Valentina. Università degli Studi di Firenze; Italia
dc.description.fil
Fil: Tedde, Andrea. Università degli Studi di Firenze; Italia
dc.description.fil
Fil: Tartaglia, Maria Carmela. University of Toronto; Canadá
dc.description.fil
Fil: Surace, Ezequiel Ignacio. Consejo Nacional de Investigaciones Científicas y Técnicas; Argentina. Fundación para la Lucha Contra las Enfermedades Neurológicas de la Infancia. Instituto de Investigaciones Neurológicas "Raúl Carrea"; Argentina
dc.description.fil
Fil: Sato, Christine. University of Toronto; Canadá
dc.description.fil
Fil: Moreno, Danielle. University of Toronto; Canadá
dc.description.fil
Fil: Xi, Zhengrui. University of Toronto; Canadá
dc.description.fil
Fil: Hung, Rachel. University of Toronto; Canadá
dc.description.fil
Fil: Nalls, Mike A.. National Institute on Aging; Estados Unidos
dc.description.fil
Fil: Singleton, Andrew. National Institute on Aging; Estados Unidos
dc.description.fil
Fil: George Hyslop, Peter St.. University of Toronto; Canadá. University of Cambridge; Reino Unido
dc.description.fil
Fil: Savchenko, Ekaterina. University of Toronto; Canadá
dc.journal.title
Neurobiology of Aging

dc.relation.alternativeid
info:eu-repo/semantics/altIdentifier/doi/http://dx.doi.org/10.1016/j.neurobiolaging.2014.07.038
dc.relation.alternativeid
info:eu-repo/semantics/altIdentifier/url/https://www.sciencedirect.com/science/article/pii/S0197458014005077
dc.relation.alternativeid
info:eu-repo/semantics/altIdentifier/url/https://www.ncbi.nlm.nih.gov/pmc/articles/PMC4268030/
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